Trabecular juvenile ossifying fibromas (JTOFs) are uncommon aggressive benign neoplasms frequently involving the maxilla. Reports of JTOFs involving the entire maxilla in children 5 years or younger are exceptionally rare. Although various treatment options for maxillary reconstruction exist, there is no consensus on best practices following JOF resection. In this case study, we present a young girl with an extensive JTOF managed with a single-stage total maxillectomy and reconstruction utilizing split calvarial bone grafting and bilateral temporalis muscle flaps.
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