An accessory mandible is a rare congenital anomaly that requires multidisciplinary management. This case report describes a female patient with an unusual accessory mandible, a dysplastic overgrowth of bone, containing teeth that extended from the midsymphyseal region. A submucosal cleft palate and cleft of the lower lip were also present. Her treatment plan took a staged approach with initial surgical resection of the accessory bone and teeth. The second stage, still in the planning phase, will correct the secondary deformity of an anterior open bite and will restore the missing lower anterior teeth. The original deformity and subsequent growth are discussed with the relevant literature.
AntoniadesK.KarakasisD.ElephtheriadesJ.Bifid mandibular condyle resulting from a sagittal fracture of the condylar head. Br J Oral Maxillofac Surg.1993; 31: 124–126.
BarrM.Jr. Facial duplication: case, review, and embryogenesis. Teratology.1982; 25: 153–159.
12.
BatraP.DuggalR.ParkashH.Non-syndromic multiple supernumerary teeth transmitted as an autosomal dominant trait. J Oral Pathol Med.2005; 34: 621–625.
13.
BellR.C.A child with two tongues. Br J Plast Surg.1971; 24: 193–196.
14.
BiasibettiE.D'AngeloA.BellinoC.GayL.GianellaP.CapucchioM.T.Diprosopia/dicephalia in calves in northern Italy: clinical and aetio-pathological features. Anat Histol Embryol.2011; 40: 433–440.
Borzabadi-FarahaniA.Orthodontic considerations in restorative management of hypodontia patients with endosseous implants. J Oral Implantol. doi: 10.1563/AAID-JOI-D-11-00022.
17.
Borzabadi-FarahaniA.YenS.L.YamashitaD.D.Sanchez-LaraP.A.Bilateral maxillary duplication: case report and literature review. Oral Surg Oral Med Oral Pathol Oral Radiol Endod. doi: 10.1016/j.tripleo.2011.06.017.
18.
ByardR.W.JimenezC.L.CarpenterB.F.SmithC.R.Congenital teratomas of the neck and nasopharynx: a clinical and pathological study of 18 cases. J Paediatr Child Health.1990; 26: 12–16.
19.
CelebilerO.SonmezA.ErdimM.OzekM.NumanoğluA.Atypical midline cleft with duplication of the metopic suture. J Craniomaxillofac Surg.2007; 35: 81–83.
20.
CameronA.C.McKellarG.M.WidmerR.P.A case of neurocristopathy that manifests facial clefting and maxillary duplication. Oral Surg Oral Med Oral Pathol.1993; 75: 338–342.
21.
ChandraR.Congenital duplication of lip, maxilla, and palate. Br J Plast Surg.1978; 31: 46–47.
22.
DanielsJ.S.IqbalA.Post-traumatic bifid condyle associated with temporomandibular joint ankylosis: report of a case and review of the literature. Oral Surg Oral Med Oral Pathol Oral Radiol Endod.2005; 99: 682–688.
23.
DaviesD.MorrisonG.MillerB.H.Reduplication of the mouth and mandible. Br J Plast Surg.1973; 26: 84–89.
24.
DepewM.J.LufkinT.RubensteinJ.L.Specification of jaw subdivisions by Dlx genes. Science.2002; 298: 381–385.
25.
de SalesM.A.do AmaralJ.I.de AmorimR.F.de Almeida FreitasR.Bifid mandibular condyle: case report and etiological considerations. J Can Dent Assoc.2004; 70: 158–162.
26.
D'SouzaR.N.RuestL-BHintonR.J.SvobodaK.K.H.Development of the craniofacial complex. In: BronnerF.Farach-CarsonM.C.RoachH.I., eds. Bone and Development.London: Springer; 2010: 153–181. Topics in Bone Biology. Vol. 6.
27.
FarmandM.Mandibular condylar head duplication. A case report. J Maxillofac Surg.1981; 9: 59–60.
HrdlickaA.Lower jaw: double condyles. Am J Phys Anthropol.1941; 28: 75–89.
41.
InchingoloF.TatulloM.AbenavoliF.M.MarrelliM.InchingoloA.D.GentileM.InchingoloA.M.DipalmaG.Non-syndromic multiple supernumerary teeth in a family unit with a normal karyotype: case report. Int J Med Sci.2010; 7: 378–384.
MaiselsD.O.Reduplication of the mouth and mandible. Br J Plast Surg.1981; 34: 23–25.
48.
MaruottiG.M.PaladiniD.NapolitanoR.MazzarelliL.L.RussoT.QuarantelliM.D'ArmientoM.R.MartinelliP.Prenatal 2D and 3D ultrasound diagnosis of diprosopus: case report with post-mortem magnetic resonance images (MRI) and review of the literature. Prenat Diagn.2009; 29: 992–994.
49.
McLaughlinC.R.Reduplication of mouth, tongue and mandible. Br J Plast Surg.1948; 1: 89–95.
50.
ObwegeserH.L.WeberG.FreihoferH.P.SailerH.F.Facial duplication: the unique case of Antonio. J Maxillofac Surg.1978; 6: 179–198.
51.
OrhanA.I.OzerL.OrhanK.Familial occurrence of nonsyndromal multiple supernumerary teeth. A rare condition. Angle Orthod.2006; 76: 891–897.
PeacockZ.S.ResnickC.M.FaquinW.C.KabanL.B.Accessory mandibular condyle at the coronoid process. J Craniofac Surg.2011; 22: 2168–2171.
54.
Pengiran SuhailiD.N.SomasundaramS.LauS.H.AjuraA.J.RoslanA.R.RamliR.Duplication of lower lip and mandible—a rare diprosopus. Int J Pediatr Otorhinolaryngol.2011; 75: 131–133.
55.
PriceJ.E.JrZaremH.A.Duplication of the mandible. Plast Reconstr Surg.1979; 64: 104–105.
RobertsonN.R.Apparent duplication of the upper alveolar process and dentition. Br Dent J.1970; 129: 333–334.
58.
SchierM.B.A.The temporomandibular joint: a consideration of its probable functional and dysfunctional sequele and report: condyle—double head—in a living person. Dent Items Interest.1948; 70: 1095–1109.
59.
ShaikhM.F.NaikN.ShahC.Duplication of hemi mandible and oral cavity, presentation of an adult patient—a case report. J Plast Reconstr Aesthet Surg.2008; 61: 183–185.
60.
ShrikiJ.LevR.WongB.F.SundineM.J.HassoA.N.Bifid mandibular condyle: CT and MR imaging appearance in two patients: case report and review of the literature. AJNR Am J Neuroradiol.2005; 26: 1865–1868.
