We are describing a case of a 14-year-old girl who developed acute cerebral infarction which was documented on diffusion-weighted magnetic resonance imaging (DWI). On detailed evaluation, diagnosis of cerebral proliferative angiopathy (CPA) was made. Incidentally, she had capillary malformation on the forehead contralateral to cerebral vascular malformation. To our knowledge, this is the first case of CPA in the literature where DWI abnormality was due to acute cerebral infarction.
LasjauniasPLLandrieuPRodeschG, et al. Cerebral proliferative angiopathy. Clinical and angiographic description of an entity different from cerebral AVMs. Stroke2008; 39: 878–85.
2.
LiuPLvXLvM, et al. Cerebral proliferative angiopathy: Clinical, angiographic features and literature review.Interv Neuroradiol2016; 22: 101–107.
3.
EllisMJArmstrongDDirksPB.Large vascular malformation in a child presenting with vascular steal phenomenon managed with pial synangiosis. J Neurosurg Pediatr2011; 7: 15–21.
4.
GoldJJCrawfordJR.Acute hemiparesis in a child as a presenting symptom of hemispheric cerebral proliferative angiopathy. Case Rep Neurol Med2013; 2013: 920859.
5.
KonoKTeradaT.Encephaloduroarteriosynangiosis for cerebral proliferative angiopathy with cerebral ischemia.J Neurosurg2014; 121: 1411–1415.
6.
DucreuxDLacourMCPDupuchKM, et al. MR perfusion imaging in a case of cerebral proliferative angiopathy.Eur Radiol2002; 12: 2717–2722.
7.
FierstraJSpiethSTranL, et al. Severely impaired cerebrovascular reserve in patients with cerebral proliferative angiopathy.J Neurosurg Pediatr2011; 8: 310–315.
8.
HongKSLeeJIHongSC.Cerebral proliferative angiopathy associated with haemangioma of the face and tongue. J Neurol Neurosurg Psychiatry2010; 81: 36–37.
9.
KhwajaGABohraVDuggalA, et al. Cerebral proliferative angiopathy: Rare case of seizures, bone erosion, and pulsatile head bump.Neurology2015; 84; 2462–2463.
10.
KringsTGeibprasertSLuoCB, et al. Segmental neurovascular syndromes in children. Neuroimaging Clin N Am2007; 17: 245–258.
11.
BhattacharyaJJLuoCBSuhDC, et al. Wyburn-Mason or Bonnet–Dechaume–Blanc as cerebrofacial arteriovenous metameric syndromes (CAMS): A new concept and a new classification. Interv Neuroradiol2001; 7: 5–17.