A case of Pisa syndrome in a 60-year-old man with dementia, probably of the Alzheimer type, who had never been exposed to any psychotropic medication is described. He also had some extrapyramidal features and myoclonus. Treatment with amantadine was slightly beneficial. We believe that this report is the first of its kind. (J Geriatr Psychiatry Neurol 1991;4:48-51).
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References
1.
Ekbom K., Lindhom H., Ljungberg L.: New dystonic syndrome associated with butyrophenone therapy. Z Neurol1972;202: 94-103.
2.
Pilette WL: Pisa syndrome, or pleurothotonus, letter. Am J Psychiatry1987;144:969-970.
3.
Yassa R.: The Pisa syndrome: A report of two cases. Br J Psychiatry1985;146:93-95.
Guy N., Raps A., Assael M.: The Pisa syndrome during maintenance antipsychotic therapy, letter . Am J Psychiatry1986; 143:1492.
6.
Chui Hfk, Li SW, Lee S.: Pisa syndrome in a Chinese patient. Aust N Z J Psychiatry1989;23:127-128.
7.
Amore M., Cerisoli M., Campanile S., et al: Pisa syndrome: Report of a case. Ital J Neurol Sci1988;9:273-274.
8.
Davidson M., Powchik P., Davis KL: Pisa syndrome in Alzheimer's disease. Biol Psychiatry1988;23:209-214.
9.
McKhann G., Drachman D., Folstein M., et al: Clinical diagnosis of Alzheimer's disease: Report of the NINCDS-ADRDA work group under the auspices of Department of Health and Human Services task force on Alzheimer's disease. Neurology1984 ;34:939-944.
10.
Folstein MR , Folstein SE, McHugh PR: Mini-Mental State: A practical method for grading the cognitive state of patients for the clinician . J Psychiatr Res1975;12:189-198.
11.
Pearce J.: The extrapyramidal disorder of Alzheimer's disease. Eur Neurol1974;12:94-103.
12.
Molsa PK, Martilla RJ, Rinne UK: Extrapyramidal signs in Alzheimer's disease. Neurology1984;34:1114-1116.
13.
Faden AI, Townsend JJ: Myoclonus in Alzheimer's disease. Arch Neurol1976;33:278-280.
14.
Mayeux R., Stern Y., Spanton S.: Heterogeneity in dementia of the Alzheimer type: Evidence of subgroups . Neurology1985;35:453-461.
15.
Steele JC, Richardson JC, Olszewski J.: Progressive supranuclear palsy: A heterogenous degeneration involving the brain stem, basal ganglia and cerebellum with vertical gaze and pseudobulbar palsy, nuchal dystonia and dementia. Arch Neurol1964;10:333-359.
16.
Davis PH, Bergeron C., McLachlan DR: Atypical presentation of progressive supranuclear palsy. Ann Neurol1985 ;17:337-343.
17.
Adams RD, Bugaert L van, van der Eecken H.: Striato-nigral degeneration. J Neuropathol Exp Neurol1964;23:584-608.
18.
Hansen L., Salmon D., Galasko D., et al: The Lewy body variant of Alzheimer's disease: A clinical and pathological entity. Neurology1990;40:1-8.
19.
Burke RE, Fahn S., Jankovic J., et al: Tardive dystonia: Late-onset and persistent dystonia caused by antipsychotic drugs. Neurology1982;32:1335-1346.
20.
Nasrallah HA , Pappas NJ, Crowe RR: Oculogyric dystonia in tardive dyskinesia . Am J Psychiatry1980;137:850-851.
21.
Gardos G.: Dystonic reactions during maintenance antipsychotic therapy. Am J Psychiatry1981;138:114-115.
22.
Munetz MR: Oculogyric crises and tardive dyskinesia. Am J Psychiatry1980;137:1628.
23.
Remington GJ : The Pisa syndrome: Possible role for serotonin and noradrenaline, letter. J Clin Psychopharmacol1988 ;8:228-229.
24.
Burke RE, Fahn S., Jankovic J., et al: Tardive dystonia and inappropriate use of neuroleptic drugs, letter. Lancet1982;1:1299.
25.
Kwentus JA, Schulz SC, Hart RP: Tardive dystonia, catatonia and electroconvulsive therapy. J Nerv Ment Dis1984;172: 171-173.
26.
Kang UJ, Burke RE, Fahn S.: Natural history and treatment of tardive dystonia. Mov Disord1986;1:193-208.
27.
Adityanjee, Jayaswal SK, Chan TM, et al: Temporary remission of tardive dystonia following electroconvulsive therapy. Br J Psychiatry1990;156:433-435.
