A fifty-three-year-old woman presented with coronary artery aneurysm in association with Osler-Weber-Rendu disease (hereditary hemorrhagic telangiec tasia) manifested also by large pulmonary arteriovenous fistulas. The arterial dye dilution curves were unusually distorted owing to the right-to-left shunts. The coronary artery aneurysm was located in multiple sites but was not accom panied by stenotic lesions. Coronary artery aneurysm without stenosis is a rare pathologic state and has not been previously reported in association with heredi tary telangiectasia.
Rath S., Har-Zahav Y., Battler A., et al: Fate of nonobstructive aneurysmatic coronary artery disease: Angiographic and clinical follow-up report. Am Heart J109:785-791, 1985.
3.
Lande A., Bedford A., Shechter LS: The spectrum of arteriographic findings in Osler-Weber-Rendu disease . Angiology27:223-240, 1976.
4.
Befeler B., Aranda JM, Embi A., et al: Coronary artery aneurysms. Study of their etiology, clinical course and effect on left ventricular function and prognosis. Am J Med62:597-607, 1977.
5.
Seabra-Gomes R., Somerville J., Ross DN, et al: Congenital coronary artery aneurysms . Br Heart J36:329-335, 1974.
6.
Falsetti HL, Caroll RJ: Coronary artery aneurysm. A review of the literature with a report of 11 new cases. Chest69:630-636, 1976.
